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Indomethacin induced and prostaglandin relieved coarctation of the aorta in right aortic arch with left arterial duct: a case report

Published online by Cambridge University Press:  06 March 2017

Stevi Golden-Plotnik
Affiliation:
Department of Paediatrics, Western University, London, Ontario, Canada
Herschel C. Rosenberg
Affiliation:
Department of Paediatrics, Western University, London, Ontario, Canada
Luis A. Altamirano-Diaz*
Affiliation:
Department of Paediatrics, Western University, London, Ontario, Canada
*
Correspondence to: Dr L. A. Altamirano-Diaz, Department of Paediatrics, Western University, 800 Commissioner’s Road East Room B5-122D London, Ontario, Canada, N6A 5W9. Tel: +519 685 8500, Ext 56061; Fax: +519 685 8334; E-mail: laltamir@uwo.ca

Abstract

We describe the case of an infant with DiGeorge syndrome born with a right aortic arch and left arterial duct. Despite the remote location of the right aortic arch from the left arterial duct, he developed coarctation of the aorta during treatment with indomethacin. This was relieved by prostaglandin treatment. This case highlights the fact that, even in the absence of an arterial duct, ductal tissue can still be present in the aorta, and cause coarctation when exposed to indomethacin. We also demonstrate the utility of prostaglandin for relief of this type of obstruction.

Type
Brief Report
Copyright
© Cambridge University Press 2017 

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