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Tracheopathia chondro-osteoplastica – an unusual cause of stridor

Published online by Cambridge University Press:  15 October 2008

R S Natt ,
T Helliwell  and
M McCormick
R S Natt*
Affiliation:
Department of Ear, Nose and Throat, Royal Liverpool University Hospital, UK
T Helliwell
Affiliation:
Department of Histopathology, Royal Liverpool University Hospital, UK
M McCormick
Affiliation:
Department of Ear, Nose and Throat, Royal Liverpool University Hospital, UK
*
Address for correspondence: Mr R S Natt, Department of Ear, Nose and Throat, Royal Liverpool University Hospital, Prescot Street, Liverpool L7 8XP, UK. E-mail: ravindernatt@hotmail.com
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Abstract

Objectives:

A case of tracheopathia chondro-osteoplastica causing sub-glottic stenosis is described.

Study design:

Case report and literature review.

Materials and methods:

A 37-year-old man presented with a 15-year history of gradually worsening dyspnoea and stridor due to sub-glottic stenosis. His medical and radiographic records were reviewed. This patient's presentation, histopathological findings and radiology images are presented and discussed.

Results:

Histopathological evaluation of microlaryngoscopy biopsy specimens, taken during laser debulking of the stenosis, confirmed the presence of tracheopathia chondro-osteoplastica.

Conclusions:

This is the first reported case of sub-glottic stenosis caused by tracheopathia chondro-osteoplastica which required an urgent tracheostomy.

Keywords

TracheaDyspnoeaStridorTracheostomy
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 123 , Issue 9 , September 2009 , pp. 1039 - 1041
Copyright
Copyright © JLO (1984) Limited 2008

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Footnotes

Presented at the North of England Otolaryngology Society Meeting, Royal Liverpool Children's NHS Trust, Alder Hey Hospital, Liverpool, March 2008.

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