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Left bronchial compression and pulmonary hypertension related to anomalous right pulmonary artery

Published online by Cambridge University Press:  22 February 2016

Jennifer A. Su*
Affiliation:
Department of Pediatrics, Division of Cardiology, Children’s Hospital of Los Angeles, Los Angeles, California, United States of America
Andrew L. Cheng
Affiliation:
Department of Pediatrics, Division of Cardiology, Children’s Hospital of Los Angeles, Los Angeles, California, United States of America
Jacqueline R. Szmuszkovicz
Affiliation:
Department of Pediatrics, Division of Cardiology, Children’s Hospital of Los Angeles, Los Angeles, California, United States of America
*
Correspondence to: J. A. Su, MD, Children’s Hospital of Los Angeles, 4650 W. Sunset Blvd, Mailstop #34, Los Angeles, CA 90027, United States of America. Tel: +323 361 8308; Fax: +323 361 1513; E-mail: jsu@chla.usc.edu

Abstract

Anomalous origin of a pulmonary artery from the ascending aorta is a congenital defect that can be complicated by pulmonary arterial hypertension, typically due to vascular disease if the anomaly is left uncorrected past 6 months of age. We describe a unique case of severe pulmonary arterial hypertension with this defect in a 1-month-old infant unexpectedly caused instead by bronchial compression from her dilated left pulmonary artery.

Type
Brief Reports
Copyright
© Cambridge University Press 2016 

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References

1. Kutsche, LM, Van Mierop, LH. Anomalous origin of a pulmonary artery from the ascending aorta: associated anomalies and pathogenesis. Am J Cardiol 1988; 61: 850856.CrossRefGoogle ScholarPubMed
2. Fraentzel, O. Ein fall von abnormer communication der aorta mit der arteria pulmonalis. Arch Pathol Anat 1868; 43: 420426.CrossRefGoogle Scholar
3. Keane, JF, Maltz, D, Bernhard, WF, Corwin, RD, Nadas, AS. Anomalous origin of one pulmonary artery from the ascending aorta. Diagnostic, physiological and surgical considerations. Circulation 1974; 50: 588594.CrossRefGoogle ScholarPubMed
4. Nigam, A, Trehan, V, Agarwal, S. Bilateral pulmonary vein stenting through an unligated vertical vein in a postoperative case of TAPVC. J Card Surg 2014; 29: 705708.CrossRefGoogle Scholar
5. Nathan, M, Rimmer, D, Piercey, G, et al. Early repair of hemitruncus: excellent early and late outcomes. J Thorac Cardiovasc Surg 2007; 133: 13291335.CrossRefGoogle ScholarPubMed
6. Robotin, MC, Bruniaux, J, Serraf, A, et al. Unusual forms of tracheobronchial compression in infants with congenital heart disease. J Thorac Cardiovasc Surg 1996; 112: 415423.CrossRefGoogle ScholarPubMed
7. Kussman, BD, Geva, T, McGowan, FX. Cardiovascular causes of airway compression. Paediatr Anaesth 2004; 14: 6074.CrossRefGoogle ScholarPubMed
8. Park, SH, Park, SY, Kim, NK, et al. Bronchial compression in an infant with isolated secundum atrial septal defect associated with severe pulmonary arterial hypertension. Korean J Pediatr 2012; 55: 297300.CrossRefGoogle Scholar
9. Ben-Shachar, G, Beder, SD, Liebman, J, Van Heeckeren, D. Hemitruncal sling: a newly recognized anomaly and its surgical correction. J Thorac Cardiovasc Surg 1985; 90: 146148.CrossRefGoogle ScholarPubMed
10. Rosa, U, Wade, KC. Bronchoscopic findings in hemitruncus. Thorax 1988; 43: 214215.CrossRefGoogle ScholarPubMed