Hostname: page-component-8448b6f56d-wq2xx Total loading time: 0 Render date: 2024-04-18T17:22:22.978Z Has data issue: false hasContentIssue false
  • English
  • Français

Fibromuscular dysplasia of the coronary arteries: a rare cause of death in infants and young children

Published online by Cambridge University Press:  14 May 2015

Carolin Mogler ,
Wolfgang Springer  and
Matthias Gorenflo
Carolin Mogler*
Affiliation:
Institute of Pathology, University Hospital Heidelberg, Germany
Wolfgang Springer
Affiliation:
Department of Pediatric Cardiology, University Hospital Heidelberg, Germany
Matthias Gorenflo
Affiliation:
Department of Pediatric Cardiology, University Hospital Heidelberg, Germany
*
Correspondence to: Dr C. Mogler, Institute of Pathology, Im Neuenheimer Feld 224, 69120 Heidelberg, Germany. Tel: +496 221 563 8175; Fax: +49 622 156 5251; E-mail: Carolin.Mogler@med.uni-heidelberg.de
Get access Rights & Permissions [Opens in a new window]

Abstract

Fibromuscular dysplasia is a common vascular disease, which mainly affects the renal arteries. In this study, we report the case of a 1-day-old infant who presented with severe left ventricular dysfunction immediately after birth, and subsequently died 3 days postnatally. At autopsy, an extensive myocardial infarction of the left ventricle and the septum was found, caused by an isolated fibromuscular dysplasia of left coronary artery.

Keywords

Fibromuscular dysplasiacoronary arterymyocardial infarctioncause of death in infants
Type
Brief Reports
Information
Cardiology in the Young , Volume 26 , Issue 1 , January 2016 , pp. 202 - 205
Check for updates
Copyright
© Cambridge University Press 2015 

Access options

Get access to the full version of this content by using one of the access options below. (Log in options will check for institutional or personal access. Content may require purchase if you do not have access.)

References

1. Slovut, D, Olin, J. Fibromuscular dysplasia. N Engl J Med 2004; 350: 1862–1871.Google Scholar
2. Olin, JW, Sealove, BA. Diagnosis, management, and future developments of fibromuscular dysplasia. J Vasc Surg 2011; 53: 826–836.Google Scholar
3. Olin, JW, Froehlich, J, Gu, X, et al. The United States registry for fibromuscular dysplasia: results in the first 447 patients. Circulation 2012; 125: 3182–3190.Google Scholar
4. Michelis, KC, Olin, JW, Kadian-Dodov, D, D’Escamard, V, Kovacic, JC. Coronary artery manifestations of fibromuscular dysplasia. J Am Coll Cardiol 2014; 64: 1033–1046.CrossRefGoogle ScholarPubMed
5. Imamura, M, Yokoyama, S, Kikuchi, K. Coronary fibromuscular dysplasia presenting as sudden infant death. Arch Pathol Lab Med 1997; 121: 159–161.Google ScholarPubMed
6. Ishikawa, Y, Sekiguchi, K, Akasaka, Y, et al. Fibromuscular dysplasia of coronary arteries resulting in myocardial infarction associated with hypertrophic cardiomyopathy in Noonan’s syndrome. Hum Pathol 2003; 34: 282–284.Google Scholar
7. Tullu, MS, Vaideeswar, P, Bhandare, D, Deshmukh, CT. Isolated coronary arterial dysplasia in an infant. Int J Cardiol 2002; 83: 169–170.CrossRefGoogle ScholarPubMed
8. Camuglia, A, Manins, V, Taylor, A, Hengel, C. Case report and review: epicardial coronary artery fibromuscular dysplasia. Heart Lung Circ 2009; 18: 151–154.CrossRefGoogle ScholarPubMed
9. Ogawa, T, Nomura, A, Komatsu, H, et al. Fibromuscular dysplasia involving coronary arteries – a case report. Angiology 1999; 50: 153–156.Google Scholar
10. Huizar, JF, Awasthi, A, Kozman, H. Fibromuscular dysplasia and acute myocardial infarction: evidence for a unique clinical and angiographic pattern. J Invasive Cardiol 2006; 18: 99–101.Google ScholarPubMed