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Bilateral coronary ostial atresia in a patient with pulmonary atresia and ventricular septal defect

Published online by Cambridge University Press:  08 March 2021

Atsuko Kato Open the ORCID record for Atsuko Kato [Opens in a new window] ,
Kimihiko Yoshii ,
Hiroshi Nishikawa  and
Hajime Sakurai
Atsuko Kato*
Affiliation:
Department of Pediatric Cardiology, Japan Community Health Organization Chukyo Hospital, Minami-ku, Nagoya, Japan
Kimihiko Yoshii
Affiliation:
Department of Pediatric Cardiology, Japan Community Health Organization Chukyo Hospital, Minami-ku, Nagoya, Japan
Hiroshi Nishikawa
Affiliation:
Department of Pediatric Cardiology, Japan Community Health Organization Chukyo Hospital, Minami-ku, Nagoya, Japan
Hajime Sakurai
Affiliation:
Department of Cardiovascular Surgery, Japan Community Health Organization Chukyo Hospital, Minami-ku, Nagoya, Japan
*
Author for correspondence: Dr A. Kato, MD, Department of Pediatric Cardiology, Japan Community Health Organization Chukyo Hospital, 1-10 Sanjo, Minami-ku, Nagoya, 457-8510, Japan. Tel: +81-52-691-7151; Fax: +81-52-692-5220. E-mail: atsukatou-ngi@umin.acjp
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Abstract

This is a case of a female infant with bilateral coronary ostial atresia associated with pulmonary atresia and ventricular septal defect. She developed coronary ischemia at 1-month of age, when she underwent an aortopulmonary shunt and an aorta-right ventricle shunt. The double-orifice tricuspid valve was separating the right ventricle from the left ventricle. She required extracorporeal cardiopulmonary support because of ventricular dysfunction and mitral regurgitation. Although she was temporarily weaned off the support after mitral valvuloplasty, she died from multiple organ failure. To the best of our knowledge, bilateral coronary ostial atresia associated with pulmonary atresia with ventricular septal defect has not been reported previously.

Keywords

Double-orifice tricuspid valveright ventricle-dependent coronary circulationhypoplastic right ventricle
Type
Images in Congenital Cardiac Disease
Information
Cardiology in the Young , Volume 31 , Issue 4 , April 2021 , pp. 644 - 645
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Copyright
© The Author(s), 2021. Published by Cambridge University Press

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References

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