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Lipomatous atrial septal hypertrophy associated with adrenocorticotropin hormone administration in an infant with West syndrome

Published online by Cambridge University Press:  05 January 2021

Moises Rodriguez-Gonzalez*
Affiliation:
Pediatric Cardiology Department, Puerta del Mar University Hospital, Cadiz, Spain
Helena M. Cascales-Poyatos
Affiliation:
Department of Pediatrics, Motril-San Antonio Primary Care Center, Motril, Granada, Spain
Ana Castellano-Martinez
Affiliation:
Pediatric Nephrology Department, Puerta del Mar University Hospital, Cadiz, Spain
Myriam Ley-Martos
Affiliation:
Pediatric Neurology Department, Puerta del Mar University Hospital, Cadiz, Spain
Alvaro Antonio Perez-Reviriego
Affiliation:
Department of Pediatrics, Motril-San Antonio Primary Care Center, Motril, Granada, Spain
*
Author for correspondence: Moises Rodriguez-Gonzalez, Pediatric Cardiology Department, Puerta del Mar University Hospital, Ana de Viya Avenue 21, Cadiz11009, Spain. Tel: +34 956002700. Email: doctormoisesrodriguez@gmail.com

Abstract

We present the rare case of lipomatous atrial septal hypertrophy associated with adrenocorticotropin hormone therapy in an infant with West syndrome, highlighting their relatively benign nature and good prognosis in children, and the relevance of the differential diagnosis with more dangerous cardiac masses in order to avoid aggressive diagnostic and therapeutic interventions.

Type
Brief Report
Copyright
© The Author(s), 2021. Published by Cambridge University Press

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References

Laura, MD, Donnino, R, Kim, EE, Benenstein, R, Freedberg, RS, Saric, M. Lipomatous atrial septal hypertrophy: a review of its anatomy, pathophysiology, multimodality imaging, and relevance to percutaneous interventions. J Am Soc Echocardiogr 2016; 29: 717723.CrossRefGoogle ScholarPubMed
Heyer, CM, Kagel, T, Lemburg, SP, Bauer, TT, Nicolas, V. Lipomatous hypertrophy of the interatrial septum. A prospective study of incidence, imaging findings, and clinical symptoms. Chest 2003; 124: 20682073.CrossRefGoogle ScholarPubMed
Rodriguez-Gonzalez, M, Castellano-Martinez, A, Grujic, B, Prieto-Heredia, MA. Disopyramide as rescue treatment in a critically ill infant with obstructive hypertrophic cardiomyopathy refractory to beta blockers. J Cardiol Cases 2017; 15: 209213.CrossRefGoogle Scholar
Jiang, J, Zhang, J, Kang, M, Yang, J. Transient hypertrophic cardiomyopathy and hypertension associated with hydrocortisone in preterm infant: a case report. Med (Baltimore) 2019; 98: e16838.CrossRefGoogle ScholarPubMed
Thédenat, B, Léauté-Labrèze, C, Boralevi, F, et al. Surveillance tensionnelle des nourrissons traités par corticothérapie générale pour un hémangiome [Blood pressure monitoring in infants with hemangiomas treated with corticosteroids]. Ann Dermatol Venereol 2002; 129: 183185.Google Scholar
Prior, JT. Lipomatous hypertrophy of cardiac interatrial septum: a lesion resembling hibemoma, lipoblastomatosis and infiltrating lipoma. Arch Pathol 1964; 78: 1115.Google Scholar
Nadra, I. Lipomatous hypertrophy of the ineratrial septum; a commonly misdiagnosed mass often leading to unnecessary cardiac surgery. Heart 2004; 90: 66.CrossRefGoogle ScholarPubMed
O’Connor, S, Recavarren, R, Nichols, LC, Parwani, AV. Lipomatous hypertrophy of the interatrial septum: an overview. Arch Pathol Lab Med 2006; 130: 397399.CrossRefGoogle ScholarPubMed
Illade, L, Plaza, M, Molina, B, et al. Lipomatous hypertrophy of the interatrial septum, an unusual tachycardia etiology in a hematopoietic stem cell transplanted patient. Pediatr Hematol Oncol 2017; 34: 131132.CrossRefGoogle Scholar
Tutar, E, Çiftçi, Ö, Fitoz, S, et al. Lipomatous hypertrophy of the interatrial septum in a child with atrial tachycardia. Pediatr Int 2016; 58: 523525.CrossRefGoogle Scholar